Bilateral hamstring origin calcification: rare presentation of Gitelman syndrome

This case report is the first case to our knowledge of intratendinous or peritendinous calcification reported in Gitelman syndrome (GS) patients. GS represents the clinical manifestations of inactivation of the Slc12a3 genes encoding the thiazide-sensitive sodium chloride cotransporter and the Trpm6-Mg genes encoding the magnesium transporters in the distal convoluted tubule. Hence, the biochemical findings resemble those with thiazide diuretics such as hypokalaemia, hypomagnesaemia, hypocalciuria, metabolic alkalosis and low normal blood pressure. Serum calcium and phosphate levels are usually unaffected in GS unless associated with hyperparathyroidism or other hypercalcaemic aetiologies. We report a 69-year-old male patient with a history of GS who presented with bilateral ischial tuberosity tenderness. Further investigations confirmed the calcification of bilateral hamstring origin. Chondrocalcinosis is a known association of GS; however, extra-articular calcification is rare. Literature review illustrates sclerochoroidal calcification as the only reported soft tissue calcification apart from chondrocalcinosis.

[1]  A. Agapito,et al.  Gitelman syndrome and primary hyperparathyroidism: a rare association , 2018, BMJ Case Reports.

[2]  M. Cervellera,et al.  Acute pancreatitis due to a Bochdalek hernia in an adult patient , 2018, BMJ Case Reports.

[3]  J. Sayer,et al.  Chondrocalcinosis and Gitelman syndrome. , 2016, QJM : monthly journal of the Association of Physicians.

[4]  V. Mishra,et al.  Management of a severe case of Gitelman syndrome with poor response to standard treatment , 2016, BMJ Case Reports.

[5]  A. Imhoff,et al.  Clinical principles in the management of hamstring injuries , 2015, Knee Surgery, Sports Traumatology, Arthroscopy.

[6]  P. Niemi,et al.  Expert opinion: diagnosis and treatment of proximal hamstring tendinopathy. , 2015, Muscles, ligaments and tendons journal.

[7]  F. Candan,et al.  Gitelman’s syndrome associated with chondrocalcinosis: a case report , 2013, Renal failure.

[8]  K. Muir,et al.  Association between low cortical bone mineral density, soft-tissue calcification, vascular calcification and chondrocalcinosis: a case-control study , 2013, Annals of the rheumatic diseases.

[9]  R. Awatramani,et al.  Dysregulation of Local Stem/Progenitor Cells as a Common Cellular Mechanism for Heterotopic Ossification , 2009, Stem cells.

[10]  T. Reynolds,et al.  Sclerochoroidal calcification associated with Gitelman syndrome and calcium pyrophosphate dihydrate deposition , 2005, Journal of Clinical Pathology.

[11]  E. Pascual,et al.  Intracellular and extracellular CPPD crystals are a regular feature in synovial fluid from uninflamed joints of patients with CPPD related arthropathy , 2005, Annals of the rheumatic diseases.

[12]  王满宜,et al.  Heterotopic ossification , 2004 .

[13]  J. Shields Sclerochoroidal calcification in calcium pyrophosphate dihydrate deposition disease (pseudogout) , 1997, Archives of ophthalmology.

[14]  L. Pasquale,et al.  Central retinal vein occlusion in a young child with cyanotic heart disease. , 1997, Archives of ophthalmology.

[15]  D. Mccarty,et al.  Stimulation of inorganic pyrophosphate elaboration by cultured cartilage and chondrocytes. , 1989, Archives of biochemistry and biophysics.

[16]  M. Dalinka,et al.  Calcification in soft tissues. , 1983, JAMA.

[17]  Dia Shehab,et al.  Heterotopic ossification. , 2002, Journal of nuclear medicine : official publication, Society of Nuclear Medicine.

[18]  J. Casez,et al.  Evidence for disturbed regulation of calciotropic hormone metabolism in gitelman syndrome. , 1995, The Journal of clinical endocrinology and metabolism.