Type IIA2 urethral duplication: report of an unusual case

This report describes a rare case of type IIA2 sagittal urethral duplication. The presentation, investigation, and management of this rare anomaly are briefly discussed. A 3½-year-old boy presented with urinary obstruction and recurrent urinary tract infection due to a stenosed dorsal urethra and segmental stenosis of the dominant ventral urethra. The child also had left-sided vesicoureteric reflux. Staged surgical management consisted of an initial vesicostomy followed by serial dilatation of the ventral urethral stricture, left ureteric reimplantation, and a 2-cm long distal urethrourethrostomy between the dorsal urethra, opening at the tip of the penis, and the ventral urethra, which had a hypospadic opening at the base of the glans. The functional and cosmetic outcomes were satisfactory. The management needs to be individualized as best suited for the patient.

[1]  H. Acharya,et al.  Urethral duplication in children: our experience of eight cases. , 2009, Journal of pediatric urology.

[2]  J. Corcos,et al.  Urethral duplication in the male: review of 16 cases. , 2000, The Journal of urology.

[3]  R. Medel,et al.  Urethral duplication in children: surgical treatment and results. , 1998, The Journal of urology.

[4]  S. Bauer,et al.  Complete patent duplication of the urethra. , 1986, The Journal of urology.

[5]  P. Ransley,et al.  Urethral duplication and complete bladder exstrophy. , 1985, The Journal of urology.

[6]  H. J. Abrams,et al.  Complete duplication of male urethra in children. , 1980, Urology.

[7]  E. Effmann,et al.  Duplication of the urethra. , 1976, Radiology.

[8]  D. Mehan,et al.  Urethral duplication, with associated agenesis of left kidney and right ureteral ectopia. , 1975, Urology.

[9]  K. Durrani,et al.  Interurethral fenestration for a case of double urethra with hypospadias. , 1973, The Journal of urology.

[10]  D. Shurtleff,et al.  Urinary reflux via the vas deferens: unusual cause of epididymitis in infancy. , 1972, The Journal of pediatrics.

[11]  R. Sesenna [On urethral duplication]. , 1960, Minerva urologica.

[12]  T. Yanai,et al.  Minimally invasive repair of hypospadiac urethral duplication , 2010, Pediatric Surgery International.

[13]  G. González Landa,et al.  [Complete duplication of the urethra]. , 1990, Archivos espanoles de urologia.

[14]  D. Williams,et al.  Urethral duplications in the male. , 1975, European urology.

[15]  R. Hargis Duplication of the male urethra. , 1972, Southern medical journal (Birmingham, Ala. Print).