Medical management of acromegaly due to ectopic production of growth hormone-releasing hormone by a carcinoid tumor.

A 59-yr-old woman with a disseminated carcinoid tumor was evaluated for acromegaly. She had previously undergone a hypophysectomy for acromegaly and an enlarged pituitary, with a reduction in her serum GH levels from 100 to 4 micrograms/L. Recurrence of acromegalic symptoms 2 yr later was accompanied by elevated serum GH (16 micrograms/L) and insulin-like growth factor I (IGF-I; 528 micrograms/L) and plasma GHRH levels (12 micrograms/L; normal, less than 30 ng/L). Computed tomographic scan did not reveal pituitary enlargement. Metastatic carcinoid tissue in bone removed at biopsy contained GHRH (100 pg/mg tissue). High performance liquid chromatography of plasma GHRH revealed predominantly GHRH-(3-40)-OH, a biologically inactive GHRH metabolite, along with mature GHRH forms, while carcinoid tissue contained both GHRH-(1-40)-OH and GHRH-(1-44)-NH2. Treatment with pergolide initially resulted in reduction in serum GH and IGF-I levels and amelioration of symptoms of acromegaly. However, after 14 months of pergolide therapy, serum GH levels increased despite administration of up to 1000 micrograms pergolide/day. Plasma GHRH levels remained elevated throughout the treatment period. Subsequent treatment with SMS 201-995, a long-acting somatostatin analog, for over 1 yr resulted in sustained reductions of ectopic GHRH secretion, GH hypersecretion, and IGF-I levels. Plasma GHRH levels correlated with simultaneously measured serum GH levels in response to acute SMS 201-995 administration. SMS 201-995 was an effective medical treatment for acromegaly caused by ectopic GHRH production in this patient.

[1]  L. Frohman,et al.  Comparison of the sensitivity of growth hormone secretion to somatostatin in vivo and in vitro in acromegaly. , 1988, The Journal of clinical endocrinology and metabolism.

[2]  P. Gorden,et al.  The response of serum growth hormone levels to the long-acting somatostatin analog SMS 201-995 in acromegaly. , 1987, The Journal of clinical endocrinology and metabolism.

[3]  L. Frohman,et al.  Rapid enzymatic degradation of growth hormone-releasing hormone by plasma in vitro and in vivo to a biologically inactive product cleaved at the NH2 terminus. , 1986, The Journal of clinical investigation.

[4]  A. Hoffman,et al.  Reduction of pituitary size by the somatostatin analogue SMS 201-995 in a patient with an islet cell tumour secreting growth hormone releasing factor. , 1986, Acta endocrinologica.

[5]  S. Lamberts,et al.  Long-term treatment of acromegaly with the somatostatin analogue SMS 201-995. , 1985, The New England journal of medicine.

[6]  W. Daughaday A new treatment for an old disease. , 1985, The New England journal of medicine.

[7]  J. Wass,et al.  Characterisation by high performance liquid chromatography of circulating growth hormone releasing factors in a human plasma. , 1985, Journal of Endocrinology.

[8]  R. Fahlbusch,et al.  TREATMENT OF METASTASISING GRF-PRODUCING TUMOUR WITH A LONG-ACTING SOMATOSTATIN ANALOGUE , 1984, The Lancet.

[9]  A. Frantz,et al.  Pergolide for the treatment of pituitary tumors secreting prolactin or growth hormone. , 1983, The New England journal of medicine.

[10]  N. Ling,et al.  Invivo biological potency of rat and human growth hormone-releasing factor and fragments of human growth hormone-releasing factor , 1983 .

[11]  N. Ling,et al.  Human hypothalamic growth hormone releasing factor (GRF): evidence for two forms identical to tumor derived GRF-44-NH2 and GRF-40. , 1983, Biochemical and biophysical research communications.

[12]  G. Braunstein,et al.  Pathophysiology of acromegaly. , 1983, Endocrine reviews.

[13]  W. Vale,et al.  Characterization of a growth hormone-releasing factor from a human pancreatic islet tumour , 1982, Nature.

[14]  N. Ling,et al.  Growth hormone-releasing factor from a human pancreatic tumor that caused acromegaly. , 1982, Science.

[15]  K. Kovacs,et al.  Somatotroph hyperplasia. Successful treatment of acromegaly by removal of a pancreatic islet tumor secreting a growth hormone-releasing factor. , 1982, The Journal of clinical investigation.

[16]  P. Marbach,et al.  SMS 201-995: a very potent and selective octapeptide analogue of somatostatin with prolonged action. , 1982, Life sciences.

[17]  M. Stachura,et al.  Partial purification and characterization of a peptide with growth hormone-releasing activity from extrapituitary tumors in patients with acromegaly. , 1980, The Journal of clinical investigation.